Functional activity of epidermal growth factor receptors in autosomal recessive polycystic kidney disease. Sweeney, William E., and Ellis D. Avner. Department of Pediatrics, Rainbow Babies and Children_s Hospital and Case Western Reserve University, Cleveland Ohio
APStracts 5:0099F, 1998.
Evidence from a number of laboratories suggests a potential role for the epidermal growth factor (EGF)/ transforming growth factor alpha (TGF-[alpha])/ epidermal growth factor receptor (EGF-R) axis in promoting epithelial hyperplasia, and cyst formation in ARPKD. As previously reported, in the CPK, BPK, and ORPK murine models of ARPKD, as well as in human ARPKD and human ADPKD, the EGF-R is mislocated to the apical surface of cystic collecting tubule (CT) epithelial cells. The present studies demonstrate that cells from cystic and control CT can be isolated, and that these cells maintain their in vivo EGF-R phenotype, in vitro. Domain specific high affinity ligand binding was assessed by standard Scatchard analysis and selective ligand stimulation of apical versus basolateral EGF-R in these cells was followed by measurement of receptor autophosphorylation, and determination of cell proliferation. These studies demonstrate that, in vitro, apically expressed EGF-Rs exhibit high affinity binding for EGF, autophosphorylate in response to EGF and transmit a mitogenic signal when stimulated by the appropriate ligand.

Received 28 January 1998; accepted in final form 13 May 1998.
APS Manuscript Number F19-8.
Article publication pending Am. J. Physiol. (Renal Physiology).
ISSN 1080-4757 Copyright 1998 The American Physiological Society.
Published in APStracts on 16 June 1998